Over the years, a number of infectious agents have been implicated as potential role players in the development of MS. Today, attention focuses primarily on HHV-6A, HHV-6B, Epstein Barr virus (EBV), Varicella Zoster Virus (VZV), Chlamydia pneumonia (Cpn) and human endogenous retroviruses (HERVs). Since these viruses and pathogens are also known to potentiate each other, it is possible that there are many infections involved in a chain reaction, resulting in an autoimmune process that continues long after the initial infections have passed. An excellent review on HHV-6 & MS was published in 2014 by Leibovitch & Jacobson.


Below are a few highlighted findings from the literature on the proposed relationship between HHV-6 and MS

  • HHV-6A/B IgG correlates with relapse and progression in MS (Ortega-Madueno 2014)
  • HHV-6A lytic antigen is target of HHV-6 specific oligcolonal bands in MS (Alenda 2014)
  • HHV-6A infection causes persistent neuroinflammation via TLR9 in CD46 transgenic mice (Reynaud 2014)
  • HHV-6 IgG but not EBV antibody titers predict relapse in multiple sclerosis (Simpson 2012)
  • MS patients have increased prevalence and titer of IgG antibodies reactive to HHV-6 U94/REP Protein (Ben Fredj 2013)
  • Marmosets inoculated with HHV-6A exhibit neurologic symptoms similar to those observed in patients with multiple sclerosis (Leibovitch 2013)
  • HHV-6 DNA is found in the plasma and serum of 25-30% of MS patients, but not in controls (Garcia Montojo 2014, Alvarez-Lafuente 2008, Hollsberg 2005)
  • HHV-6 IgG but not EBV antibody titers predict relapse in multiple sclerosis (Simpson 2012)
  • MS patients have increased prevalence and titer of IgG antibodies reactive to HHV-6 U94/REP Protein (Ben Fredj 2013
  • Marmosets inoculated with HHV-6A exhibit neurologic symptoms similar to those observed in patients with multiple sclerosis (Leibovitch 2013)
  • HHV-6 DNA is found in the plasma and serum of 25-30% of MS patients, but not in controls (Garcia Montojo 2011, Alvarez-Lafuente 2008, Hollsberg 2005)
  • HHV-6 specific intrathecal antibodies have been observed in MS patients but not healthy controls (Derfuss 2005, Ferro 2012)
  • HHV-6 & EBV reactive oligoclonal bands have been found in nearly 1/3 of MS patients, but rarely among patients with other neurological syndromes (Virtanen 2011, Virtanen 2013)
  • More HHV-6 DNA is found in MS patient serum during exacerbations than during relapses (Behzad-Behbahani 2011Alvarez-Lafuente 2006, Alvarez-Lafuente 2004)
  • HHV-6A reactivation has been linked to two genes associated with an increased risk for MS: IRF5 and MHC2TA rs4774C (Dominguez-Mozo 2012, Garcia-Montojo 2011)
  • HHV-6 serum DNA levels diminish with interferon beta treatment and patients who do not clear their HHV-6 infection during interferon therapy have a poor prognosis (Garcia-Montojo 2011)
  • More HHV-6 DNA is found in MS plaques than in non-affected white matter by immunohistochemistry and FISH in local tissue PCR (Goodman 2003)
  • Lymphoproliferative response to HHV-6A: 67% of MS patients have significant lymphocyte response to HHV-6 vs. 32% of controls (Soldan 2000)
  • T-cells reacting with myelin basic protein cross-react with HHV-6 and EBV synthetic peptides (Cheng 2012)

Etiological Theories

“Molecular mimicry” involving HHV-6 has been proposed as one mechanism by which the autoimmune process could be triggered and eventually progress toward the development of MS. One study showed that certain residues on the HHV-6 genome are identical to residues of myelin basic protein. Importantly, both T-cells and antibody responses to this peptide sequences were found elevated in MS patients (Tejada-Simon 2003). Moreover, in vitro infection of glial precursor cells was found to impair cell replication and increase the expression of oligodendrocyte markers, suggesting that HHV-6 infection of the CNS may influence the neural repair mechanism (Dietrich 2004).

In addition, it is known that the binding of HHV-6 to its primary cellular receptor CD46 can bias the cytokine profile of specific T-cell responses, which could in turn contribute to the CNS tissue damage observed in MS (Yao 2010). Furthermore, the leading theory of CMV-induced autoimmunity in transplant patients is that cell surface proteins from CMV-infected tissues are incorporated into the viral envelope of CMV, inducing graft-versus-host disease post transplant. Similarly, an argument could be made that myelin proteins from infected oligodendrocytes could become incorporated into the HHV-6A envelope as they enter and leave the cell, thus inducing the CNS autoimmunity observed in conditions such as MS and CFS.


Limiting Factors

One of the obstacles preventing further study of HHV-6A in serum of MS patients is that current commercial assays are not sensitive enough to detect the virus in cases of low-grade chronic infection (See Testing). However, four studies in the late 1990s (when such an assay was briefly available), showed dramatic differences between patients with MS and controls without MS. Studies using assays that differentiate between active and latent virus have shown an exceptionally strong association between HHV-6A and MS. We now know that due to the high level of latent virus found in controls, active infection should be measured by looking for HHV-6 DNA in cell free serum or plasma. Thanks to the advent of more sensitive detection technologies such as ddPCR, assays are now in development that will be able to effectively identify active HHV-6A infection in MS patients.


HHV-6A as a potential treatment target for MS patients

Once active HHV-6A infections can be diagnosed in MS patients through the use of more sensitive assays in commercial laboratories, MS may become treatable to some degree through the use of antiviral and immune modulators in properly identified patients. Such treatment has the potential to drastically improve CNS function in patients with MS symptoms attributable to HHV-6A viremia. At the 2013 International Conference on HHV-6 & 7, several groups met to discuss this issue, and agreed that a clinical trial of HHV-6A antiviral therapy for the treatment of MS patients is warranted and urgently needed. These groups are now focused on organizing such a trial.


Key Papers: HHV-6 & Multiple Sclerosis

Alenda

2014

Identification of the major HHV-6 antigen recognized by CSF IgG in MS.
Broccolo

2013

Possible role of HHV-6 as a trigger of autoimmune disease.
Broccolo

2013

Selective reactivation of HHV-6 in patients with autoimmune connective tissue diseases.
Virtanen

2013

Oligoclonal bands in MS reactive against two herpesviruses and association with MRI findings.
Leibovitch

2013

Novel Marmoset model of HHV-6A and HHV-6B infections: Immunologic, Virologic and Radiologic Characterization.
Ben-Fredj

2013

Prevalence of HHV U94/REP antibodies and DNA in Tunisian multiple sclerosis patients.
Dominguez-Mozo

2012

MHC2TA mRNA levels and HHV-6 in MS patients treated with interferon beta along two-year follow-up.
Simpson

2012

Anti-HHV-6 IgG titer significantly predicts subsequent relapse risk in multiple sclerosis.
Virtanen

2012

Viruses and Multiple Sclerosis.
Ferro

2012

Active intrathecal herpes simplex virus type 1 (HSV-1) and human herpesvirus-6 (HHV-6) infection at onset of multiple sclerosis.
Ben-Fredj

2012

Identification of human herpesviruses 1 to 8 in Tunisian multiple sclerosis patients and healthy blood donors.
Cheng

2012

Cross-reactivity of autoreactive T cells with MBP and viral antigens in patients with MS.
Nora-Krukle

2011

HHV-6 & HHV-7 reactivation and disease activity in multiple sclerosis.
Khaki

2011

Evaluation of viral antibodies in Iranian multiple sclerosis patients.
Vandenbroeck

2011

Validation of IRF5 as multiple sclerosis risk gene: putative role in interferon beta therapy and human herpes virus-6 infection.
Garcia-Montojo

2011

Human herpesvirus 6 and effectiveness of interferon beta 1b in multiple sclerosis patients.
Behzad-Behbahani

2011

Human herpesvirus-6 viral load and antibody titer in serum samples of patients with multiple sclerosis.
Virtanen

2011

Intrathecal human herpesvirus 6 antibodies in multiple sclerosis and other demyelinating diseases presenting as oligoclonal bands in cerebrospinal fluid.
Behzad-Behbahani

2009

Human herpesvirus-6 viral load and antibody titer in serum samples of patients with multiple sclerosis.
Ahram

2009

Association between human herpesvirus 6 and occurrence of multiple sclerosis among Jordanian patients.
Alvarez-Lafuente

2008

Herpesviruses and human endogenous retroviral sequences in the cerebrospinal fluid of multiple sclerosis patients.
Martínez

2007

Environment-gene interaction in multiple sclerosis: human herpesvirus 6 and MHC2TA.
Alvarez-Lafuente

2006

Clinical parameters and HHV-6 active replication in relapsing-remitting multiple sclerosis patients.
Hollsberg

2005

Presence of Epstein-Barr virus and human herpesvirus 6B DNA in multiple sclerosis patients: associations with disease activity.
Derfuss

2005

Intrathecal antibody (IgG) production against human herpesvirus type 6 occurs in about 20% of multiple sclerosis patients and might be linked to a polyspecific B-cell response.
Alvarez-Lafuente

2004

Relapsing-remitting multiple sclerosis and human herpesvirus 6 active infection.
Dietrich

2004

Infection with an endemic human herpesvirus disrupts critical glial precursor cell properties.
Okada

2004

Mechanisms underlying fatigue: a voxel-based morphometric study of chronic fatigue syndrome.
Tejada-Simon

2003

Cross-reactivity with myelin basic protein and human herpesvirus-6 in multiple sclerosis.
Chapenko

2003

Correlation between HHV-6 reactivation and multiple sclerosis disease activity.
Goodman

2003

Human herpesvirus 6 genome and antigen in acute multiple sclerosis lesions.
Berti

2002

Increased detection of serum HHV-6 DNA sequences during multiple sclerosis (MS) exacerbations and correlation with parameters of MS disease progression.
Soldan

2000

Increased lymphoproliferative response to human herpesvirus type 6A variant in multiple sclerosis patients.
Ablashi

2000

Frequent HHV-6 reactivation in multiple sclerosis (MS) and chronic fatigue syndrome (CFS) patients.
Ablashi

1998

Human Herpesvirus-6 (HHV-6) infection in multiple sclerosis: a preliminary report.
Soldan

1997

Association of human herpes virus 6 (HHV-6) with multiple sclerosis: increased IgM response to HHV-6 early antigen and detection of serum HHV-6 DNA.
Challoner

1995

Plaque-associated expression of human herpesvirus 6 in multiple sclerosis.
Patnaik

1995

Prevalence of IgM antibodies to human herpesvirus 6 early antigen (p41/38) in patients with chronic fatigue syndrome.